Surgical management of an isolated symptomatic talonavicular coalition: a paediatric perspective
- 1 Department of Paediatric Orthopaedic Surgery, Evelina London Children's Hospital, London, UK
- 2 King's College London Faculty of Life Sciences and Medicine, London, UK
- Correspondence to Michail Kokkinakis; michail.kokkinakis@gstt.nhs.uk
Abstract
Talonavicular (TN) coalition is a rare pathological union of the talus and navicular bones. We report the case of a 7-year-old girl with a symptomatic TN coalition, who underwent operative management with a lateral column lengthening procedure using autologous iliac crest bone grafting. There are no complications to report and the graft was incorporated at an early stage. At 3 year follow-up the patient has remained pain-free since the operation and maintained alignment. To our knowledge, this is the first reported case of TN coalition treated with reconstructive surgery in a paediatric patient.
Background
Tarsal coalition is the abnormal bony, fibrous or cartilaginous union between two or more tarsal bones apparent in 1%–2% of the population.1–3 Coalition of the calcaneonavicular and talocalcaneal joints are the most frequently encountered. Importantly, coalition is asymptomatic in up to 75% of individuals which results in underdiagnosis.4 Ossification of the coalition can contribute to the development of symptoms which typically present during adolescence.
Talonavicular (TN) coalition is a rare subtype with an incidence of less than 1.3% of all tarsal coalitions.1 5 TN coalition is almost exclusively congenital, related to a failure of differentiation and segmentation in embryological mesenchymal tissue.4 6 TN coalitions are mostly asymptomatic, with the chief complaint in symptomatic patients being a painful medial navicular prominence.7 Associated structural abnormality includes hindfoot valgus, forefoot abduction and loss of the medial arch. These deformities place extra stress on the adjacent soft tissue and midfoot structures.
The most common treatment for TN coalition is analgesia and orthotics.8 Steroid and local anaesthetic injections have a role in establishing the site of pain and alleviating symptoms temporarily. Few instances of operative management of symptomatic TN coalition have been reported in case studies. Debridement of the prominent medial mass and fusion of the calcaneocuboid and subtalar joints to treat secondary arthritis have been performed.5 7 9 10 We present a paediatric case of TN coalition refractory to non-operative management, leaving surgical intervention as the only recourse. To our knowledge, this report presents the first paediatric case of hindfoot reconstructive surgery for symptomatic TN coalition.
Case report
Presentation
A 4-year-old girl (now aged 10) was referred by the family practitioner with a medial prominence of the right foot. The child reported mild discomfort without limitation of function. She was otherwise fit and healthy with no relevant family history. Examination yielded a flexible flatfoot with forefoot abduction and a rigid hindfoot. Isolated tenderness was elicited at the medial prominence.
Investigations
The initial radiographs demonstrate a plano-valgus right foot with a complete osseous talonavicular coalition and a prominent medial navicular mass (figures 1 and 2). Bilateral MRI scans were conducted to assess the coalition, identify any associated pathology and compare to the contralateral side (figure 3A,B). There was minimal bone oedema at the site of the coalition, with no associated tendinopathy or evidence of concurrent tarsal coalition.
Weight bearing lateral radiograph of right foot demonstrating talonavicular coalition and pes planus(flatfoot).

Weight bearing anterior-posterior radiograph of right foot demonstrating talonavicular coalition and medial navicular prominence (yellow dotted line).

Sagittal T1 weighted stir MRI of both feet. (A) – right foot demonstrating talonavicular coalition (TNC). (B) – left foot demonstrating normal talonavicular anatomy (T=talus, n=navicular).

Treatment
Initial treatment was non-operative with analgesia and orthotics. The patient developed progressive medial prominence pain, callosity, difficulty with footwear and limitation of sports activity over the ensuing 3 years from her initial clinical encounter. At the age of 7, a shared decision was made to undergo reconstructive foot surgery. Surgical treatment was principled on the pathoanatomical and biomechanical features of the deformity.
The procedure was conducted under general anaesthesia with antibiotic prophylaxis and the use of an intra-operative image intensifier. An Ollier’s incision was utilised and the lateral calcaneus exposed. Two-millimetre Kirschner wires (K-wires) were introduced in a retrograde manner from the distal cuboid into the distal calcaneus, proximal to the proposed osteotomy site, to prevent subluxation of the calcaneo-cuboid joint during lengthening.
The modified Evans calcaneal osteotomy as popularised by Mosca was utilised.11 An oblique, proximal-lateral to distal-medial extra-articular osteotomy of the anterior process of the calcaneus was performed at the isthmus of the calcaneus (narrowest cranio-caudal region). The osteotomy was approximately 2 cm posterior to the calcaneocuboid joint, ending medially between the anterior and middle facets of the subtalar joint. The osteotomy was distracted using laminar spreaders until satisfactory clinical (absence of midfoot break) and radiological correction (coverage of exposed talonavicular coalesced bone by the medial cuneiform) was achieved. The distraction gap was measured at 15 mm and a corresponding graft was harvested. An ipsilateral tricortical trapezoid autologous iliac crest bone graft measuring 15 mm by 20 mm by 5 mm was sited at the osteotomy. The graft was secured by advancing the retrograde K-wires into the proximal calcaneus (figures 4 and 5). The patient was placed in a below-knee cast and advised not to bear weight for 6 weeks. At the end of this period, the K-wires were removed in the clinic and progressive weight-bearing in a walker boot was commenced.
Intra-operative image intensifier picture demonstrating laminar spreader opening calcaneal osteotomy site.

Intra-operative image intensifier picture demonstrating grafted osteotomy site secured with K-wires.

Outcome and follow-up
The patient had an uneventful recovery with post-operative radiographs demonstrating complete graft union and coverage of the medial bony prominence, resulting in resolution of the midfoot break following lateral column lengthening (figure 6). Three years following her right foot procedure she remains asymptomatic with no functional limitation and full participation in physical activities.
20 week post-op anterior-posterior radiograph of the foot demonstrating adequate medial navicular coverage (yellow dotted line) by the medial cuneiform as a result of the lateral column lengthening procedure (red arrow shows the healed lengthening calcaneal osteotomy).

Discussion
TN coalition is commonly bilateral, however, it can also occur in isolation as in the present case. Although easily overseen, most cases of TN coalition can be diagnosed using plain radiographs. Radiological features include the absence of the talonavicular joint space, rounding of the naviculo-cuneiform joint and a mushroom sign on antero-posterior foot view.12 13 In the paediatric setting, TN coalition could be misinterpreted as a prominent navicular or an accessory navicular, therefore familiarity with growth plate and tarsal anatomy is vital when interpreting radiographs.
The technique of lateral column lengthening is established in the treatment of paediatric flatfoot associated with a valgus hindfoot and forefoot abduction.14 The lengthening affords correction by medial translation of the mobile forefoot over the fixed hindfoot. In routine cases of a flatfoot without TN coalition, the navicular is translated medially providing adequate cover to the exposed talar head, resulting in improved talonavicular coverage. In the present case, the senior author (MK) used these principles to provide coverage of the symptomatic exposed medial coalesced talonavicular bone, resulting in the abolition of the prominent midfoot break and symptom resolution.
Alternative surgical procedures include arthrodesis for symptomatic secondary degenerative disease in adult TN coalition.5 9 10 The limitation of this procedure in the paediatric setting is a violation of articular surfaces and growth plates, resulting in secondary deformity and non-resolution of medial symptoms. Similarly, medial mass debridement is limited in application as this provides only local treatment to the prominent medial break, and does not address the underlying structural pathologies of forefoot abduction and hindfoot valgus.7 The modified Evans lateral column lengthening benefits have utility in skeletally immature patients, while also addressing the structural deformity and preserving the range of motion in the residual tarsal complex. This technique is originally described in patients over 10 years of age, although it can also be utilised on younger patients with significant refractory symptoms as it does not violate growth plates or articular surfaces.14 We are mindful that the patient is yet to reach skeletal maturity and she will remain under annual follow-up until this time.
In summary, TN coalition is a rare condition that seldom presents with symptoms. In cases of symptomatic TN coalition, it is imperative to fully assess the pathology and any associated foot deformity to offer optimal treatment. In cases refractory to non-operative management, when considering surgery there is paucity in the literature regarding treatment options. We present a unique case of lateral column lengthening for TN coalition in a paediatric patient with excellent clinical and radiological outcomes 3 years following surgery.
Learning points
-
Tarsal coalition is a condition where two or more of the tarsal bones are fused by bone (synostosis), cartilage (synchondrosis) or fibrous tissue (syndesmosis) which typically presents around the time of skeletal maturation.
-
Talonavicular coalition is a rare subtype which can be easily overseen on radiographs.
-
In the paediatric setting unfamiliarity with growth plate anatomy on radiographs can lead to diagnostic uncertainty. Furthermore, the coalition can be misinterpreted as a prominent navicular or an accessory type navicular.
-
Despite the majority being bilateral, this case illustrates a unique case of unilateral talonavicular coalition in a patient with no associated dysmorphic features.
-
Surgical treatment should be based on the principles of the pathoanatomical and biomechanical features of the deformity rather than simple separation of the coalition.
-
Lateral column lengthening has afforded an excellent correction and mid-term outcome in the present case.
Ethics statements
Patient consent for publication
Footnotes
-
Contributors KP and AK contributed equally to this paper. AP contributed to this manuscript. MK was the lead surgeon on the case and is the senior author on this report.
-
Funding The authors have not declared a specific grant for this research from any funding agency in the public, commercial or not-for-profit sectors.
-
Competing interests None declared.
-
Provenance and peer review Not commissioned; externally peer reviewed.
- © BMJ Publishing Group Limited 2021. No commercial re-use. See rights and permissions. Published by BMJ.
References
Use of this content is subject to our disclaimer